Monday, September 16, 2013

0 Schnitzler"s syndrome: diagnosis, treatment, and follow-up


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Schnitzler’s syndrome: diagnosis, treatment, and follow-up


Abstract



Schnitzler’s syndrome is characterized by recurrent urticarial rash and monoclonal gammopathy, associated with clinical and biological signs of inflammation and a long-term risk of AA amyloidosis and overt lymphoproliferation. An extensive literature review was performed, and the following questions were addressed during an expert meeting: In whom should Schnitzler’s syndrome be suspected? How should the diagnosis of Schnitzler’s syndrome be established? How should a patient with Schnitzler’s syndrome be treated? How should a patient with Schnitzler’s syndrome be followed up?. A diagnosis of Schnitzler’s syndrome is considered definite in any patient with two obligate criteria: a recurrent urticarial rash and a monoclonal IgM gammopathy, and two of the following minor criteria: recurrent fever, objective signs of abnormal bone remodeling, elevated CRP level or leukocytosis, and a neutrophilic infiltrate on skin biopsy. It is considered probable, if only 1 minor criterion is present. In patients with monoclonal IgG gammopathies, diagnosis is definite if three minor criteria are present and possible if two are present. First-line treatment in patients with significant alteration of quality of life or persistent elevation of markers of inflammation should be anakinra. Follow-up should include clinical evaluation, CBC and CRP every 3 months and MGUS as usually recommended.










  1. A. Simon1, 

  2. B. Asli2, 

  3. M. Braun-Falco3, 

  4. H. De Koning4, 

  5. J.-P. Fermand2, 

  6. C. Grattan5,

  7. K. Krause6, 

  8. H. Lachmann7, 

  9. C. Lenormand8, 

  10. V. Martinez-Taboada9, 

  11. M. Maurer6, 

  12. M. Peters10, 

  13. R. Rizzi11, 

  14. F. Rongioletti12, 

  15. T. Ruzicka3, 

  16. L. Schnitzler13, 

  17. B. Schubert14,

  18. J. Sibilia15, 

  19. D. Lipsker8


Article first published online: 9 MAR 2013

DOI: 10.1111/all.12129






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